Chylothorax in Gorham's Syndrome. A Common Complication of a Rare Disease

Overview

Journal Chest

Publisher Elsevier

Specialty Pulmonary Medicine

Date 1994 Jan 1

PMID 8275732

Citations 51

Authors

M L Tie

G A Poland

E C Rosenow 3rd

Affiliations

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Abstract

One hundred forty-six cases of Gorham's syndrome are documented in the literature. Twenty-five (17 percent) patients have been reported to have chylothorax as a complication. To our knowledge, this high incidence of chylothorax has not been reported previously. We describe two such patients treated by thoracic duct ligation and compared our results with others to support early surgical intervention via a low right-sided thoracotomy in these cases.

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