Surgical Management for a Huge Presacral Teratoma and a Meningocele in an Adult with Currarino Triad: a Case Report

Overview

Journal Surg Case Rep

Specialty General Surgery

Date 2018 Jan 21

PMID 29352751

Citations 4

Authors

Shigenobu Emoto

Manabu Kaneko

Koji Murono

Kazuhito Sasaki

Kensuke Otani

Takeshi Nishikawa

Toshiaki Tanaka

Keisuke Hata

Kazushige Kawai

Hideaki Imai

Nobuhito Saito

Hiroshi Kobayashi

Sakae Tanaka

Masako Ikemura

Tetsuo Ushiku

Hiroaki Nozawa

Affiliations

Soon will be listed here.

Abstract

Background: The Currarino triad is a rare hereditary syndrome comprising anorectal malformation, sacral bony defect, and presacral mass. Most of the patients are diagnosed during infancy.

Case Presentation: A 44-year-old man was diagnosed with Currarino triad, with a huge presacral teratoma and meningocele. One-stage surgery via posterior approach was successful.

Conclusions: Treatment of the presacral mass in the Currarino triad, diagnosed in adulthood, is challenging. Multidisciplinary management and detailed planning before surgery are important for a satisfactory outcome.

Citing Articles

Managing Recurrent Teratoma in Currarino Syndrome.

Chung Y, Centauri S, Nguyen T Cureus. 2023; 15(11):e48780.

PMID: 38098935 PMC: 10719879. DOI: 10.7759/cureus.48780.

Sacrococcygeal teratomas: a case-based review from the perspective of individual multidisciplinary experts.

Mosleh M, Heo T, Shin H, Sohn M Childs Nerv Syst. 2022; 39(1):57-64.

PMID: 36422695 DOI: 10.1007/s00381-022-05768-1.

Currarino syndrome in an adult woman.

Shin J, Hong D, Kim Y, Lim K, Lee K, Kim T Obstet Gynecol Sci. 2019; 62(5):367-370.

PMID: 31538082 PMC: 6737057. DOI: 10.5468/ogs.2019.62.5.367.

Adult sacrococcygeal teratoma: a retrospective study over eight years at a single institution.

Xu X, Zhao F, Cheng X, Zhong W, Liu J, Jiang W J Zhejiang Univ Sci B. 2019; 20(8):670-678.

PMID: 31273964 PMC: 6656562. DOI: 10.1631/jzus.B1800621.

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