Ruptured Hepatic Epithelioid Angiomyolipoma: a Case Report and Literature Review

Overview

Journal Case Rep Oncol

Publisher Karger

Specialty Oncology

Date 2014 Jul 3

PMID 24987358

Citations 12

Authors

Shogo Tajima

Akira Suzuki

Kiyoshi Suzumura

Affiliations

Soon will be listed here.

Abstract

A 38-year-old male was admitted to our hospital due to upper abdominal pain. Computed tomography revealed a hepatic angiomyolipoma (AML; 10.5 × 9.5 × 7.0 cm in size), which had ruptured into the space between the liver and the diaphragm. Following transcatheter arterial embolization, surgical resection was performed. The tumor consisted of epithelioid cells (50-60%), mature fat (40-50%), and thickened-wall blood vessels. Considering the amount of epithelioid cells and their positivity for E-cadherin and β-catenin, the tumor was diagnosed as hepatic epithelioid AML. Cases of ruptured hepatic AML are rare. To the best of our knowledge, this is the sixth case reported in the English literature.

Citing Articles

Transcatheter arterial embolization followed by laparoscopic anatomic hepatectomy for spontaneous rupture of a giant hepatic angiomyolipoma: a case report.

Wang J, Shi R, Luo H, Yang P, Luo H, Gao Z Front Surg. 2024; 10:1329535.

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Case report: Hepatic epithelioid angiomyolipoma with elevated alpha-fetoprotein and a history of breast cancer.

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Clinical characteristics and outcomes of patients with hepatic angiomyolipoma: A literature review.

Calame P, Tyrode G, Verhoeven D, Felix S, Klompenhouwer A, Di Martino V World J Gastroenterol. 2021; 27(19):2299-2311.

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Hepatic epithelioid angiomyolipoma: a report of two cases and review of the literature.

Feng J, Liu C, Yang X, Jiang Y, Qu Z Int J Clin Exp Pathol. 2020; 11(3):1739-1745.

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Hepatic Epithelioid Angiomyolipoma Treated with Laparoscopic Resection: Case Report and Review of the Literature.

Williams C, Hickle K, Bakke K, Jamshed S, Bozorgzadeh A Case Reports Hepatol. 2019; 2019:2362618.

PMID: 31355023 PMC: 6633875. DOI: 10.1155/2019/2362618.

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